An Unusual Complication of Congenital Diaphragmatic Hernia

A term newborn was referred to our unit with a postnatal diagnosis of a right-sided congenital diaphragmatic hernia (CDH). She was managed with high-frequency oscillatory ventilation, inotropic support, and nitric oxide, with planned surgical repair when she was medically optimized. On day 6 of life...

Full description

Bibliographic Details
Main Authors: E Tian Tan, Keren Sloan, Kokila Lakhoo
Format: Article
Language:English
Published: Georg Thieme Verlag KG 2017-01-01
Series:European Journal of Pediatric Surgery Reports
Subjects:
Online Access:http://www.thieme-connect.de/DOI/DOI?10.1055/s-0037-1607353
_version_ 1811336365877493760
author E Tian Tan
Keren Sloan
Kokila Lakhoo
author_facet E Tian Tan
Keren Sloan
Kokila Lakhoo
author_sort E Tian Tan
collection DOAJ
description A term newborn was referred to our unit with a postnatal diagnosis of a right-sided congenital diaphragmatic hernia (CDH). She was managed with high-frequency oscillatory ventilation, inotropic support, and nitric oxide, with planned surgical repair when she was medically optimized. On day 6 of life, there was an acute deterioration causing difficulty maintaining adequate ventilation and the infant requiring increasing analgesia and paralysis, especially during abdominal examination. A repeat X-ray showed distended bowel loops in the right hemithorax when compared with previous films raising suspicion of bowel obstruction. The infant proceeded to emergency laparotomy in the neonatal intensive care unit. She was found to have a right-sided Bochdalek (posterolateral) defect. The entire small bowel was within the thoracic cavity and appeared dusky secondary to obstruction caused by compression of a herniated right liver lobe against the hernia defect. Bowel perfusion improved after reduction and a BioDesign patch was used to repair the defect. The infant went on to have a straightforward recovery and was transferred to her local hospital for ongoing care on day 17. Bowel obstruction is an uncommon complication in the perinatal period in infants with CDH. A high index of suspicion for bowel compromise is needed in neonates who deteriorate acutely after a period of stabilization. Imaging should be obtained as soon as possible and early surgical intervention may be life-saving.
first_indexed 2024-04-13T17:38:24Z
format Article
id doaj.art-04dc3cee0a604c4eb11ce01654f2c646
institution Directory Open Access Journal
issn 2194-7619
2194-7627
language English
last_indexed 2024-04-13T17:38:24Z
publishDate 2017-01-01
publisher Georg Thieme Verlag KG
record_format Article
series European Journal of Pediatric Surgery Reports
spelling doaj.art-04dc3cee0a604c4eb11ce01654f2c6462022-12-22T02:37:15ZengGeorg Thieme Verlag KGEuropean Journal of Pediatric Surgery Reports2194-76192194-76272017-01-010501e65e6710.1055/s-0037-1607353An Unusual Complication of Congenital Diaphragmatic HerniaE Tian Tan0Keren Sloan1Kokila Lakhoo2Department of Paediatric Surgery, Oxford University Hospitals NHS Foundation Trust, Oxford, Oxfordshire, United Kingdom of Great Britain and Northern IrelandDepartment of Paediatric Surgery, Oxford University Hospitals NHS Foundation Trust, Oxford, Oxfordshire, United Kingdom of Great Britain and Northern IrelandDepartment of Paediatric Surgery, Oxford University Hospitals NHS Foundation Trust, Oxford, Oxfordshire, United Kingdom of Great Britain and Northern IrelandA term newborn was referred to our unit with a postnatal diagnosis of a right-sided congenital diaphragmatic hernia (CDH). She was managed with high-frequency oscillatory ventilation, inotropic support, and nitric oxide, with planned surgical repair when she was medically optimized. On day 6 of life, there was an acute deterioration causing difficulty maintaining adequate ventilation and the infant requiring increasing analgesia and paralysis, especially during abdominal examination. A repeat X-ray showed distended bowel loops in the right hemithorax when compared with previous films raising suspicion of bowel obstruction. The infant proceeded to emergency laparotomy in the neonatal intensive care unit. She was found to have a right-sided Bochdalek (posterolateral) defect. The entire small bowel was within the thoracic cavity and appeared dusky secondary to obstruction caused by compression of a herniated right liver lobe against the hernia defect. Bowel perfusion improved after reduction and a BioDesign patch was used to repair the defect. The infant went on to have a straightforward recovery and was transferred to her local hospital for ongoing care on day 17. Bowel obstruction is an uncommon complication in the perinatal period in infants with CDH. A high index of suspicion for bowel compromise is needed in neonates who deteriorate acutely after a period of stabilization. Imaging should be obtained as soon as possible and early surgical intervention may be life-saving.http://www.thieme-connect.de/DOI/DOI?10.1055/s-0037-1607353congenital diaphragmatic herniacomplicationsgastrointestinalobstructionneonatalsurgery
spellingShingle E Tian Tan
Keren Sloan
Kokila Lakhoo
An Unusual Complication of Congenital Diaphragmatic Hernia
European Journal of Pediatric Surgery Reports
congenital diaphragmatic hernia
complications
gastrointestinal
obstruction
neonatal
surgery
title An Unusual Complication of Congenital Diaphragmatic Hernia
title_full An Unusual Complication of Congenital Diaphragmatic Hernia
title_fullStr An Unusual Complication of Congenital Diaphragmatic Hernia
title_full_unstemmed An Unusual Complication of Congenital Diaphragmatic Hernia
title_short An Unusual Complication of Congenital Diaphragmatic Hernia
title_sort unusual complication of congenital diaphragmatic hernia
topic congenital diaphragmatic hernia
complications
gastrointestinal
obstruction
neonatal
surgery
url http://www.thieme-connect.de/DOI/DOI?10.1055/s-0037-1607353
work_keys_str_mv AT etiantan anunusualcomplicationofcongenitaldiaphragmatichernia
AT kerensloan anunusualcomplicationofcongenitaldiaphragmatichernia
AT kokilalakhoo anunusualcomplicationofcongenitaldiaphragmatichernia
AT etiantan unusualcomplicationofcongenitaldiaphragmatichernia
AT kerensloan unusualcomplicationofcongenitaldiaphragmatichernia
AT kokilalakhoo unusualcomplicationofcongenitaldiaphragmatichernia