A report of 2 patients with transient blindness following Le Fort I osteotomy and a review of past reported cases

Blindness following a LeFort I osteotomy is a rare but extremely serious complication. Ten cases have been reported to date. None of these patients recovered vision. Optic neuropathy is believed to be the cause but the exact mechanism has not been settled. We report the first, and the only two, docu...

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Main Authors: Philip Mathew, Hirji Sorab Adenwalla, Puthucode V Narayanan, Emily Nyamu
Format: Article
Language:English
Published: Thieme Medical Publishers, Inc. 2015-09-01
Series:Indian Journal of Plastic Surgery
Subjects:
Online Access:http://www.thieme-connect.de/DOI/DOI?10.4103/0970-0358.173129
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author Philip Mathew
Hirji Sorab Adenwalla
Puthucode V Narayanan
Emily Nyamu
author_facet Philip Mathew
Hirji Sorab Adenwalla
Puthucode V Narayanan
Emily Nyamu
author_sort Philip Mathew
collection DOAJ
description Blindness following a LeFort I osteotomy is a rare but extremely serious complication. Ten cases have been reported to date. None of these patients recovered vision. Optic neuropathy is believed to be the cause but the exact mechanism has not been settled. We report the first, and the only two, documented cases of complete loss of vision that recovered subsequently. The first patient was a 19-year-old male with repaired bilateral cleft lip and palate. He developed loss of vision in the right eye on the second postoperative day. The second patient was a 22-year-old male with repaired unilateral cleft lip and palate. He developed complete loss of vision in the left eye on the day of surgery. Both these patients underwent ongoing studies, which did not show any abnormalities. Both were treated with methylprednisolone. Both the patients gradually showed improvement in their vision. The first patient recovered normal vision several months postoperatively. The second patient’s vision improved to 4/60 by 4 months postoperatively. We discuss the probable mechanisms of optic nerve injury and also the possible reasons why sight was restored in these patients. This is a rare but serious complication following a fairly common procedure. Through this article we wish to create an awareness of this complication and also a possible way of avoiding such a disaster.
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spelling doaj.art-08cd4c96fcec4b399f08e7fab0d175062022-12-22T01:44:39ZengThieme Medical Publishers, Inc.Indian Journal of Plastic Surgery0970-03581998-376X2015-09-01480329730010.4103/0970-0358.173129A report of 2 patients with transient blindness following Le Fort I osteotomy and a review of past reported casesPhilip Mathew0Hirji Sorab Adenwalla1Puthucode V Narayanan2Emily Nyamu3Department of Plastic Surgery and Burns, The Charles Pinto Centre for Cleft Lip, Palate and Craniofacial Anomalies, Jubilee Mission Medical College and Research Institute, Thrissur, Kerala, IndiaDepartment of Plastic Surgery and Burns, The Charles Pinto Centre for Cleft Lip, Palate and Craniofacial Anomalies, Jubilee Mission Medical College and Research Institute, Thrissur, Kerala, IndiaDepartment of Plastic Surgery and Burns, The Charles Pinto Centre for Cleft Lip, Palate and Craniofacial Anomalies, Jubilee Mission Medical College and Research Institute, Thrissur, Kerala, IndiaDepartment of Plastic Surgery and Burns, The Charles Pinto Centre for Cleft Lip, Palate and Craniofacial Anomalies, Jubilee Mission Medical College and Research Institute, Thrissur, Kerala, IndiaBlindness following a LeFort I osteotomy is a rare but extremely serious complication. Ten cases have been reported to date. None of these patients recovered vision. Optic neuropathy is believed to be the cause but the exact mechanism has not been settled. We report the first, and the only two, documented cases of complete loss of vision that recovered subsequently. The first patient was a 19-year-old male with repaired bilateral cleft lip and palate. He developed loss of vision in the right eye on the second postoperative day. The second patient was a 22-year-old male with repaired unilateral cleft lip and palate. He developed complete loss of vision in the left eye on the day of surgery. Both these patients underwent ongoing studies, which did not show any abnormalities. Both were treated with methylprednisolone. Both the patients gradually showed improvement in their vision. The first patient recovered normal vision several months postoperatively. The second patient’s vision improved to 4/60 by 4 months postoperatively. We discuss the probable mechanisms of optic nerve injury and also the possible reasons why sight was restored in these patients. This is a rare but serious complication following a fairly common procedure. Through this article we wish to create an awareness of this complication and also a possible way of avoiding such a disaster.http://www.thieme-connect.de/DOI/DOI?10.4103/0970-0358.173129blindnesscomplicationshypotensive anaesthesialefort i osteotomymaxillary regression
spellingShingle Philip Mathew
Hirji Sorab Adenwalla
Puthucode V Narayanan
Emily Nyamu
A report of 2 patients with transient blindness following Le Fort I osteotomy and a review of past reported cases
Indian Journal of Plastic Surgery
blindness
complications
hypotensive anaesthesia
lefort i osteotomy
maxillary regression
title A report of 2 patients with transient blindness following Le Fort I osteotomy and a review of past reported cases
title_full A report of 2 patients with transient blindness following Le Fort I osteotomy and a review of past reported cases
title_fullStr A report of 2 patients with transient blindness following Le Fort I osteotomy and a review of past reported cases
title_full_unstemmed A report of 2 patients with transient blindness following Le Fort I osteotomy and a review of past reported cases
title_short A report of 2 patients with transient blindness following Le Fort I osteotomy and a review of past reported cases
title_sort report of 2 patients with transient blindness following le fort i osteotomy and a review of past reported cases
topic blindness
complications
hypotensive anaesthesia
lefort i osteotomy
maxillary regression
url http://www.thieme-connect.de/DOI/DOI?10.4103/0970-0358.173129
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