A rare case of dual congenital coronary cameral fistula and myocardial bridge

Abstract. Rationale:. A coronary artery fistula (CAF) is an anomalous communication between a coronary artery and a cardiac chamber or great vessel. It is a rare congenital anomaly that is often small and asymptomatic, occurring in only 0.002% of the general population. Most CAFs originate from the...

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Main Authors: Yong Shen, MD, Maya Saranathan.
Format: Article
Language:English
Published: Wolters Kluwer 2022-04-01
Series:Medicine
Online Access:http://journals.lww.com/10.1097/MD.0000000000028952
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author Yong Shen, MD
Maya Saranathan.
author_facet Yong Shen, MD
Maya Saranathan.
author_sort Yong Shen, MD
collection DOAJ
description Abstract. Rationale:. A coronary artery fistula (CAF) is an anomalous communication between a coronary artery and a cardiac chamber or great vessel. It is a rare congenital anomaly that is often small and asymptomatic, occurring in only 0.002% of the general population. Most CAFs originate from the right coronary artery and flow into the right cardiac system. Although extremely rare, some cases may originate from the bilateral coronary arteries and flow into the left ventricle. Patient concerns:. Herein, we report a rare case of a 55-year-old male smoker with no history of heart disease or cardiac surgery, who presented with a 5-year history of recurrent chest congestion, palpitations, and shortness of breath. On physical examination, his heart and lungs revealed normal findings without cardiac murmurs and no systemic or pulmonary edema. Moreover, 24-hour ambulatory electrocardiography showed no signs of ischemia but exhibited a short array of ventricular tachycardia and short atrial tachycardia. Chest computed tomography showed left apical emphysema without cardiomegaly and pulmonary congestion. Furthermore, coronary angiography revealed dual congenital coronary cameral fistula, a complex CAF with a left circumflex artery–left ventricle fistula and a right coronary artery–left ventricle fistula, complicated with a myocardial bridge. Diagnosis and interventions:. A diagnosis of left circumflex artery–left ventricle fistula complicated with a right coronary artery–left ventricle fistula and myocardial bridge was made. Since the patient refused surgery, medical management with enteric-coated aspirin, sustained-release metoprolol, and atorvastatin calcium was initiated. Outcomes and lesson:. Currently, the patient is now asymptomatic and in good condition since 6 months after undergoing conservative treatment with β-blockers.
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spelling doaj.art-2bc90efbea6f40e2b914d823bc6ae00b2022-12-22T00:30:37ZengWolters KluwerMedicine0025-79741536-59642022-04-0110116e2895210.1097/MD.0000000000028952202204220-00009A rare case of dual congenital coronary cameral fistula and myocardial bridgeYong Shen, MD0Maya Saranathan.1Department of Internal Medicine-Cardiovascular, Hechi People's Hospital, Hechi, Guangxi, China.Department of Internal Medicine-Cardiovascular, Hechi People's Hospital, Hechi, Guangxi, China.Abstract. Rationale:. A coronary artery fistula (CAF) is an anomalous communication between a coronary artery and a cardiac chamber or great vessel. It is a rare congenital anomaly that is often small and asymptomatic, occurring in only 0.002% of the general population. Most CAFs originate from the right coronary artery and flow into the right cardiac system. Although extremely rare, some cases may originate from the bilateral coronary arteries and flow into the left ventricle. Patient concerns:. Herein, we report a rare case of a 55-year-old male smoker with no history of heart disease or cardiac surgery, who presented with a 5-year history of recurrent chest congestion, palpitations, and shortness of breath. On physical examination, his heart and lungs revealed normal findings without cardiac murmurs and no systemic or pulmonary edema. Moreover, 24-hour ambulatory electrocardiography showed no signs of ischemia but exhibited a short array of ventricular tachycardia and short atrial tachycardia. Chest computed tomography showed left apical emphysema without cardiomegaly and pulmonary congestion. Furthermore, coronary angiography revealed dual congenital coronary cameral fistula, a complex CAF with a left circumflex artery–left ventricle fistula and a right coronary artery–left ventricle fistula, complicated with a myocardial bridge. Diagnosis and interventions:. A diagnosis of left circumflex artery–left ventricle fistula complicated with a right coronary artery–left ventricle fistula and myocardial bridge was made. Since the patient refused surgery, medical management with enteric-coated aspirin, sustained-release metoprolol, and atorvastatin calcium was initiated. Outcomes and lesson:. Currently, the patient is now asymptomatic and in good condition since 6 months after undergoing conservative treatment with β-blockers.http://journals.lww.com/10.1097/MD.0000000000028952
spellingShingle Yong Shen, MD
Maya Saranathan.
A rare case of dual congenital coronary cameral fistula and myocardial bridge
Medicine
title A rare case of dual congenital coronary cameral fistula and myocardial bridge
title_full A rare case of dual congenital coronary cameral fistula and myocardial bridge
title_fullStr A rare case of dual congenital coronary cameral fistula and myocardial bridge
title_full_unstemmed A rare case of dual congenital coronary cameral fistula and myocardial bridge
title_short A rare case of dual congenital coronary cameral fistula and myocardial bridge
title_sort rare case of dual congenital coronary cameral fistula and myocardial bridge
url http://journals.lww.com/10.1097/MD.0000000000028952
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