Congenital Anterior Urethrocutaneous Fistula with a Persistent Urethral Groove
Congenital anterior urethrocutaneous fistula (CAUF) is a rare penile anomaly with only 63 cases reported in the literature. The anomaly can present in isolation or in association with chordee or hypospadias. We report the case of an 8-month-old boy with CAUF that resembles the embryological urethral...
| Main Authors: | , |
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| Format: | Article |
| Language: | English |
| Published: |
Georg Thieme Verlag KG
2021-01-01
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| Series: | European Journal of Pediatric Surgery Reports |
| Subjects: | |
| Online Access: | http://www.thieme-connect.de/DOI/DOI?10.1055/s-0040-1721469 |
| _version_ | 1818935863109746688 |
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| author | Hazem Mosa Massimo Garriboli |
| author_facet | Hazem Mosa Massimo Garriboli |
| author_sort | Hazem Mosa |
| collection | DOAJ |
| description | Congenital anterior urethrocutaneous fistula (CAUF) is a rare penile anomaly with only 63 cases reported in the literature. The anomaly can present in isolation or in association with chordee or hypospadias. We report the case of an 8-month-old boy with CAUF that resembles the embryological urethral groove. On examination, a wide urethral groove was noted to cover the midshaft of the penis with a well formed urethra extending proximally and distally and with a normal glandular anatomy, a wide glandular meatus, and a complete foreskin. The urethral groove was tubularized and covered in layers. Surgery was complicated with early superficial skin dehiscence not affecting the urethral repair. Refashioning of the skin was then performed. A satisfactory aesthetic and functional outcome was observed at 7 years' follow-up. Defining the anatomy of CAUF and distal urethra is key in management of these children. |
| first_indexed | 2024-12-20T05:26:55Z |
| format | Article |
| id | doaj.art-480f78845ca54d99b910470f832aa2fc |
| institution | Directory Open Access Journal |
| issn | 2194-7619 2194-7627 |
| language | English |
| last_indexed | 2024-12-20T05:26:55Z |
| publishDate | 2021-01-01 |
| publisher | Georg Thieme Verlag KG |
| record_format | Article |
| series | European Journal of Pediatric Surgery Reports |
| spelling | doaj.art-480f78845ca54d99b910470f832aa2fc2022-12-21T19:51:51ZengGeorg Thieme Verlag KGEuropean Journal of Pediatric Surgery Reports2194-76192194-76272021-01-010901e9e1210.1055/s-0040-1721469Congenital Anterior Urethrocutaneous Fistula with a Persistent Urethral GrooveHazem Mosa0Massimo Garriboli1Department of Paediatric Urology, Evelina London Children's Hospital, London, United KingdomDepartment of Paediatric Urology, Evelina London Children's Hospital, London, United KingdomCongenital anterior urethrocutaneous fistula (CAUF) is a rare penile anomaly with only 63 cases reported in the literature. The anomaly can present in isolation or in association with chordee or hypospadias. We report the case of an 8-month-old boy with CAUF that resembles the embryological urethral groove. On examination, a wide urethral groove was noted to cover the midshaft of the penis with a well formed urethra extending proximally and distally and with a normal glandular anatomy, a wide glandular meatus, and a complete foreskin. The urethral groove was tubularized and covered in layers. Surgery was complicated with early superficial skin dehiscence not affecting the urethral repair. Refashioning of the skin was then performed. A satisfactory aesthetic and functional outcome was observed at 7 years' follow-up. Defining the anatomy of CAUF and distal urethra is key in management of these children.http://www.thieme-connect.de/DOI/DOI?10.1055/s-0040-1721469congenital anterior urethrocutaneous fistulacaufhypospadias |
| spellingShingle | Hazem Mosa Massimo Garriboli Congenital Anterior Urethrocutaneous Fistula with a Persistent Urethral Groove European Journal of Pediatric Surgery Reports congenital anterior urethrocutaneous fistula cauf hypospadias |
| title | Congenital Anterior Urethrocutaneous Fistula with a Persistent Urethral Groove |
| title_full | Congenital Anterior Urethrocutaneous Fistula with a Persistent Urethral Groove |
| title_fullStr | Congenital Anterior Urethrocutaneous Fistula with a Persistent Urethral Groove |
| title_full_unstemmed | Congenital Anterior Urethrocutaneous Fistula with a Persistent Urethral Groove |
| title_short | Congenital Anterior Urethrocutaneous Fistula with a Persistent Urethral Groove |
| title_sort | congenital anterior urethrocutaneous fistula with a persistent urethral groove |
| topic | congenital anterior urethrocutaneous fistula cauf hypospadias |
| url | http://www.thieme-connect.de/DOI/DOI?10.1055/s-0040-1721469 |
| work_keys_str_mv | AT hazemmosa congenitalanteriorurethrocutaneousfistulawithapersistenturethralgroove AT massimogarriboli congenitalanteriorurethrocutaneousfistulawithapersistenturethralgroove |