Cyclopia with shoulder dystocia leading to an obstetric catastrophe: a case report

<p>Abstract</p> <p>Introduction</p> <p>Cyclopia is a rare fetal malformation characterized by a single palpebral fissure and a proboscis associated with severe brain malformations. Approximately 1.05 in 100,000 births including stillbirths are identified as cyclopean. T...

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Main Authors: Metgud Mrityunjay C, Nilgar Baburao R, Bellad Mrutyunjaya B, Koregol Mahesh C, Durdi Geeta
Format: Article
Language:English
Published: BMC 2010-05-01
Series:Journal of Medical Case Reports
Online Access:http://www.jmedicalcasereports.com/content/4/1/160
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author Metgud Mrityunjay C
Nilgar Baburao R
Bellad Mrutyunjaya B
Koregol Mahesh C
Durdi Geeta
author_facet Metgud Mrityunjay C
Nilgar Baburao R
Bellad Mrutyunjaya B
Koregol Mahesh C
Durdi Geeta
author_sort Metgud Mrityunjay C
collection DOAJ
description <p>Abstract</p> <p>Introduction</p> <p>Cyclopia is a rare fetal malformation characterized by a single palpebral fissure and a proboscis associated with severe brain malformations. Approximately 1.05 in 100,000 births including stillbirths are identified as cyclopean. The prevalence is about one in 11,000 to 20,000 in live births and one in 250 during embryogenesis.</p> <p>Case presentation</p> <p>A 30-year-old Indian woman of Asian origin, sixth gravida, was referred to the labor room of our hospital. There were no ultrasound examinations performed during this pregnancy as our patient had not received regular antenatal care. We found out that the head of her baby was already outside the vulva but the remaining parts of the baby were not yet delivered. Further examination was carried out and a diagnosis of shoulder dystocia with intrauterine fetal demise was made. A stillborn baby boy of 3.5 kg was delivered using McRoberts' maneuver. The baby was suspected of having features of cyclopia and this was later confirmed by autopsy and anatomic correlation. The mother had a cervical tear which extended into the lower segment of her uterus, thus leading to the rupture of her uterus. There was a massive broad ligament hematoma on the left side of her uterus. A total abdominal hysterectomy was carried out.</p> <p>Conclusion</p> <p>Prenatal diagnosis by ultrasound examination might help in detecting cyclopia and preventing complications associated with this condition. However, in developing countries where women do not receive regular antenatal care and do not undergo prenatal diagnosis, such cases will go undetected. In our case report, the occurrence of shoulder dystocia could be coincidental, as no risk factors were previously noted.</p>
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spelling doaj.art-5a9244dc5ad9491fb199b0a9f0f90d092022-12-22T03:04:42ZengBMCJournal of Medical Case Reports1752-19472010-05-014116010.1186/1752-1947-4-160Cyclopia with shoulder dystocia leading to an obstetric catastrophe: a case reportMetgud Mrityunjay CNilgar Baburao RBellad Mrutyunjaya BKoregol Mahesh CDurdi Geeta<p>Abstract</p> <p>Introduction</p> <p>Cyclopia is a rare fetal malformation characterized by a single palpebral fissure and a proboscis associated with severe brain malformations. Approximately 1.05 in 100,000 births including stillbirths are identified as cyclopean. The prevalence is about one in 11,000 to 20,000 in live births and one in 250 during embryogenesis.</p> <p>Case presentation</p> <p>A 30-year-old Indian woman of Asian origin, sixth gravida, was referred to the labor room of our hospital. There were no ultrasound examinations performed during this pregnancy as our patient had not received regular antenatal care. We found out that the head of her baby was already outside the vulva but the remaining parts of the baby were not yet delivered. Further examination was carried out and a diagnosis of shoulder dystocia with intrauterine fetal demise was made. A stillborn baby boy of 3.5 kg was delivered using McRoberts' maneuver. The baby was suspected of having features of cyclopia and this was later confirmed by autopsy and anatomic correlation. The mother had a cervical tear which extended into the lower segment of her uterus, thus leading to the rupture of her uterus. There was a massive broad ligament hematoma on the left side of her uterus. A total abdominal hysterectomy was carried out.</p> <p>Conclusion</p> <p>Prenatal diagnosis by ultrasound examination might help in detecting cyclopia and preventing complications associated with this condition. However, in developing countries where women do not receive regular antenatal care and do not undergo prenatal diagnosis, such cases will go undetected. In our case report, the occurrence of shoulder dystocia could be coincidental, as no risk factors were previously noted.</p>http://www.jmedicalcasereports.com/content/4/1/160
spellingShingle Metgud Mrityunjay C
Nilgar Baburao R
Bellad Mrutyunjaya B
Koregol Mahesh C
Durdi Geeta
Cyclopia with shoulder dystocia leading to an obstetric catastrophe: a case report
Journal of Medical Case Reports
title Cyclopia with shoulder dystocia leading to an obstetric catastrophe: a case report
title_full Cyclopia with shoulder dystocia leading to an obstetric catastrophe: a case report
title_fullStr Cyclopia with shoulder dystocia leading to an obstetric catastrophe: a case report
title_full_unstemmed Cyclopia with shoulder dystocia leading to an obstetric catastrophe: a case report
title_short Cyclopia with shoulder dystocia leading to an obstetric catastrophe: a case report
title_sort cyclopia with shoulder dystocia leading to an obstetric catastrophe a case report
url http://www.jmedicalcasereports.com/content/4/1/160
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AT belladmrutyunjayab cyclopiawithshoulderdystocialeadingtoanobstetriccatastropheacasereport
AT koregolmaheshc cyclopiawithshoulderdystocialeadingtoanobstetriccatastropheacasereport
AT durdigeeta cyclopiawithshoulderdystocialeadingtoanobstetriccatastropheacasereport