Coexistence of osteopoikilosis with seronegative spondyloarthritis and Raynaud’s phenomenon: first case report with evaluation of the nailfold capillary bed and literature review
Osteopoikilosis (OPK) is a rare autosomal dominant bone disorder characterized by numerous hyperostotic areas that tend to localize in periarticular osseous regions. It is usually asymptomatic and is often diagnosed incidentally during X-rays. OPK may be an isolated finding or associated with other...
| Main Authors: | , , , , |
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| Format: | Article |
| Language: | English |
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PAGEPress Publications
2012-12-01
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| Series: | Reumatismo |
| Subjects: | |
| Online Access: | http://www.reumatismo.org/index.php/reuma/article/view/602 |
| _version_ | 1818013316300144640 |
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| author | F. Ravera E. Alessandri A. Sulli B. Ruaro M. Cutolo |
| author_facet | F. Ravera E. Alessandri A. Sulli B. Ruaro M. Cutolo |
| author_sort | F. Ravera |
| collection | DOAJ |
| description | Osteopoikilosis (OPK) is a rare autosomal dominant bone disorder characterized by numerous hyperostotic areas that tend to localize in periarticular osseous regions. It is usually asymptomatic and is often diagnosed incidentally during X-rays. OPK may be an isolated finding or associated with other pathologies,<em> e.g.</em> skin manifestations, rheumatic and/or skeletal disorders. We report a literature review and, for the first time, the coexistence of OPK with seronegative spondyloarthritis and Raynaud’s phenomenon in a 48-year old female. To the best of our knowledge, this is the first case of OPK studied by videocapillaroscopy, demonstrating the absence of specific microvascular abnormalities of nailfold capillaries. |
| first_indexed | 2024-04-14T06:31:37Z |
| format | Article |
| id | doaj.art-5b0a9dd1dcb64e3ab55aa4143234dd66 |
| institution | Directory Open Access Journal |
| issn | 0048-7449 2240-2683 |
| language | English |
| last_indexed | 2024-04-14T06:31:37Z |
| publishDate | 2012-12-01 |
| publisher | PAGEPress Publications |
| record_format | Article |
| series | Reumatismo |
| spelling | doaj.art-5b0a9dd1dcb64e3ab55aa4143234dd662022-12-22T02:07:35ZengPAGEPress PublicationsReumatismo0048-74492240-26832012-12-0164533533910.4081/reumatismo.2012.335Coexistence of osteopoikilosis with seronegative spondyloarthritis and Raynaud’s phenomenon: first case report with evaluation of the nailfold capillary bed and literature reviewF. RaveraE. AlessandriA. SulliB. RuaroM. CutoloOsteopoikilosis (OPK) is a rare autosomal dominant bone disorder characterized by numerous hyperostotic areas that tend to localize in periarticular osseous regions. It is usually asymptomatic and is often diagnosed incidentally during X-rays. OPK may be an isolated finding or associated with other pathologies,<em> e.g.</em> skin manifestations, rheumatic and/or skeletal disorders. We report a literature review and, for the first time, the coexistence of OPK with seronegative spondyloarthritis and Raynaud’s phenomenon in a 48-year old female. To the best of our knowledge, this is the first case of OPK studied by videocapillaroscopy, demonstrating the absence of specific microvascular abnormalities of nailfold capillaries.http://www.reumatismo.org/index.php/reuma/article/view/602osteopoikilosis, spondyloarthritis, Raynaud’s phenomenon, nailfold videocapillaroscopy |
| spellingShingle | F. Ravera E. Alessandri A. Sulli B. Ruaro M. Cutolo Coexistence of osteopoikilosis with seronegative spondyloarthritis and Raynaud’s phenomenon: first case report with evaluation of the nailfold capillary bed and literature review Reumatismo osteopoikilosis, spondyloarthritis, Raynaud’s phenomenon, nailfold videocapillaroscopy |
| title | Coexistence of osteopoikilosis with seronegative spondyloarthritis and Raynaud’s phenomenon: first case report with evaluation of the nailfold capillary bed and literature review |
| title_full | Coexistence of osteopoikilosis with seronegative spondyloarthritis and Raynaud’s phenomenon: first case report with evaluation of the nailfold capillary bed and literature review |
| title_fullStr | Coexistence of osteopoikilosis with seronegative spondyloarthritis and Raynaud’s phenomenon: first case report with evaluation of the nailfold capillary bed and literature review |
| title_full_unstemmed | Coexistence of osteopoikilosis with seronegative spondyloarthritis and Raynaud’s phenomenon: first case report with evaluation of the nailfold capillary bed and literature review |
| title_short | Coexistence of osteopoikilosis with seronegative spondyloarthritis and Raynaud’s phenomenon: first case report with evaluation of the nailfold capillary bed and literature review |
| title_sort | coexistence of osteopoikilosis with seronegative spondyloarthritis and raynaud s phenomenon first case report with evaluation of the nailfold capillary bed and literature review |
| topic | osteopoikilosis, spondyloarthritis, Raynaud’s phenomenon, nailfold videocapillaroscopy |
| url | http://www.reumatismo.org/index.php/reuma/article/view/602 |
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