Submandibular swelling, pulsations and otalgia due to sublingual gland and blood vessels herniation through mylohyoid boutonnière: Case report

Background/Aim: Mylohyoid boutonnière is a common anatomical variant with extremely rare clinical manifestations. We report two cases of symptomatic unilateral mylohyoid boutonnière with sublingual gland herniation. Case report: The first was a 34-year-old female with a two months history of a left...

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Main Authors: Janović Aleksa, Bracanović Đurđa, Antić Svetlana, Marković-Vasiljković Biljana
Format: Article
Language:English
Published: Balkan Stomatological Society 2022-01-01
Series:Balkan Journal of Dental Medicine
Subjects:
Online Access:https://scindeks-clanci.ceon.rs/data/pdf/2335-0245/2022/2335-02452201058J.pdf
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author Janović Aleksa
Bracanović Đurđa
Antić Svetlana
Marković-Vasiljković Biljana
author_facet Janović Aleksa
Bracanović Đurđa
Antić Svetlana
Marković-Vasiljković Biljana
author_sort Janović Aleksa
collection DOAJ
description Background/Aim: Mylohyoid boutonnière is a common anatomical variant with extremely rare clinical manifestations. We report two cases of symptomatic unilateral mylohyoid boutonnière with sublingual gland herniation. Case report: The first was a 34-year-old female with a two months history of a left submandibular swelling, intermittent pulsations, and otalgia. The second 67-year-old female presented with a left submandibular pain six months after total thyroidectomy due to papillary carcinoma. After detailed clinical and radiological evaluation by ultrasonography (US) and computed tomography (CT), the mylohyoid gap with sublingual gland herniation was diagnosed in both patients. The dynamic US with a tongue pressed down on the mouth floor revealed blood vessel compression by a herniated sublingual gland in the first patient. Conclusions: This is the first case of a mylohyoid boutonnière related intermittent vascular compression. Dynamic US and CT may help to differentiate intermittent and persistent sublingual gland herniation through the mylohyoid boutonnière from other pathological lesions in the submandibular region.
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spelling doaj.art-6142f671b68046d7b572ebecd8098fe62022-12-22T02:00:17ZengBalkan Stomatological SocietyBalkan Journal of Dental Medicine2335-02452022-01-01261586210.5937/bjdm2201058J2335-02452201058JSubmandibular swelling, pulsations and otalgia due to sublingual gland and blood vessels herniation through mylohyoid boutonnière: Case reportJanović Aleksa0Bracanović Đurđa1Antić Svetlana2https://orcid.org/0000-0002-1239-492XMarković-Vasiljković Biljana3University of Belgrade, Faculty of Dental Medicine, Department of Diagnostic Radiology, Belgrade, SerbiaUniversity of Belgrade, Faculty of Dental Medicine, Department of Diagnostic Radiology, Belgrade, SerbiaUniversity of Belgrade, Faculty of Dental Medicine, Department of Diagnostic Radiology, Belgrade, SerbiaUniversity of Belgrade, Faculty of Dental Medicine, Department of Diagnostic Radiology, Belgrade, SerbiaBackground/Aim: Mylohyoid boutonnière is a common anatomical variant with extremely rare clinical manifestations. We report two cases of symptomatic unilateral mylohyoid boutonnière with sublingual gland herniation. Case report: The first was a 34-year-old female with a two months history of a left submandibular swelling, intermittent pulsations, and otalgia. The second 67-year-old female presented with a left submandibular pain six months after total thyroidectomy due to papillary carcinoma. After detailed clinical and radiological evaluation by ultrasonography (US) and computed tomography (CT), the mylohyoid gap with sublingual gland herniation was diagnosed in both patients. The dynamic US with a tongue pressed down on the mouth floor revealed blood vessel compression by a herniated sublingual gland in the first patient. Conclusions: This is the first case of a mylohyoid boutonnière related intermittent vascular compression. Dynamic US and CT may help to differentiate intermittent and persistent sublingual gland herniation through the mylohyoid boutonnière from other pathological lesions in the submandibular region.https://scindeks-clanci.ceon.rs/data/pdf/2335-0245/2022/2335-02452201058J.pdfanatomic variationmylohyoid musclesublingual glandultrasonographycomputed tomography
spellingShingle Janović Aleksa
Bracanović Đurđa
Antić Svetlana
Marković-Vasiljković Biljana
Submandibular swelling, pulsations and otalgia due to sublingual gland and blood vessels herniation through mylohyoid boutonnière: Case report
Balkan Journal of Dental Medicine
anatomic variation
mylohyoid muscle
sublingual gland
ultrasonography
computed tomography
title Submandibular swelling, pulsations and otalgia due to sublingual gland and blood vessels herniation through mylohyoid boutonnière: Case report
title_full Submandibular swelling, pulsations and otalgia due to sublingual gland and blood vessels herniation through mylohyoid boutonnière: Case report
title_fullStr Submandibular swelling, pulsations and otalgia due to sublingual gland and blood vessels herniation through mylohyoid boutonnière: Case report
title_full_unstemmed Submandibular swelling, pulsations and otalgia due to sublingual gland and blood vessels herniation through mylohyoid boutonnière: Case report
title_short Submandibular swelling, pulsations and otalgia due to sublingual gland and blood vessels herniation through mylohyoid boutonnière: Case report
title_sort submandibular swelling pulsations and otalgia due to sublingual gland and blood vessels herniation through mylohyoid boutonniere case report
topic anatomic variation
mylohyoid muscle
sublingual gland
ultrasonography
computed tomography
url https://scindeks-clanci.ceon.rs/data/pdf/2335-0245/2022/2335-02452201058J.pdf
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AT anticsvetlana submandibularswellingpulsationsandotalgiaduetosublingualglandandbloodvesselsherniationthroughmylohyoidboutonnierecasereport
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