Non surgical management of unilateral lacrimal gland swelling in a paediatric patient of Rosai-Dorfman disease: A case report

A 10-year-old girl presented to us with inferonasally displaced, non-axial proptosis of oculus dexter (OD), with ipsilateral, painless massive cervical lymphadenopathy of ten weeks duration. After a detailed hematological work-up and imaging, the histological evidence obtained on cervical lymph node...

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Main Authors: Sailie Shirodkar, Prachi Patil, Nagendra Shah
Format: Article
Language:English
Published: Wolters Kluwer Medknow Publications 2019-01-01
Series:Indian Journal of Ophthalmology
Subjects:
Online Access:http://www.ijo.in/article.asp?issn=0301-4738;year=2019;volume=67;issue=7;spage=1236;epage=1238;aulast=
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author Sailie Shirodkar
Prachi Patil
Nagendra Shah
author_facet Sailie Shirodkar
Prachi Patil
Nagendra Shah
author_sort Sailie Shirodkar
collection DOAJ
description A 10-year-old girl presented to us with inferonasally displaced, non-axial proptosis of oculus dexter (OD), with ipsilateral, painless massive cervical lymphadenopathy of ten weeks duration. After a detailed hematological work-up and imaging, the histological evidence obtained on cervical lymph node biopsy established the diagnosis of Rosai-Dorfman disease. Although, Rosai-Dorfman disease of unilateral lacrimal gland is extremely infrequent, a high degree of suspicion is warranted in a case of young patient presenting with unilateral isolated lacrimal gland swelling and associated lymphadenopathy, wherein no other cause is found. Treatment protocol should be individualized as per the extent of systemic involvement and functional disability.
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spelling doaj.art-6a6954b04ad14bc3aa044021b3c7c6c22022-12-21T20:35:55ZengWolters Kluwer Medknow PublicationsIndian Journal of Ophthalmology0301-47381998-36892019-01-016771236123810.4103/ijo.IJO_1596_18Non surgical management of unilateral lacrimal gland swelling in a paediatric patient of Rosai-Dorfman disease: A case reportSailie ShirodkarPrachi PatilNagendra ShahA 10-year-old girl presented to us with inferonasally displaced, non-axial proptosis of oculus dexter (OD), with ipsilateral, painless massive cervical lymphadenopathy of ten weeks duration. After a detailed hematological work-up and imaging, the histological evidence obtained on cervical lymph node biopsy established the diagnosis of Rosai-Dorfman disease. Although, Rosai-Dorfman disease of unilateral lacrimal gland is extremely infrequent, a high degree of suspicion is warranted in a case of young patient presenting with unilateral isolated lacrimal gland swelling and associated lymphadenopathy, wherein no other cause is found. Treatment protocol should be individualized as per the extent of systemic involvement and functional disability.http://www.ijo.in/article.asp?issn=0301-4738;year=2019;volume=67;issue=7;spage=1236;epage=1238;aulast=Lacrimal gland swellingRosai-Dorfman diseasesinus histiocytosis
spellingShingle Sailie Shirodkar
Prachi Patil
Nagendra Shah
Non surgical management of unilateral lacrimal gland swelling in a paediatric patient of Rosai-Dorfman disease: A case report
Indian Journal of Ophthalmology
Lacrimal gland swelling
Rosai-Dorfman disease
sinus histiocytosis
title Non surgical management of unilateral lacrimal gland swelling in a paediatric patient of Rosai-Dorfman disease: A case report
title_full Non surgical management of unilateral lacrimal gland swelling in a paediatric patient of Rosai-Dorfman disease: A case report
title_fullStr Non surgical management of unilateral lacrimal gland swelling in a paediatric patient of Rosai-Dorfman disease: A case report
title_full_unstemmed Non surgical management of unilateral lacrimal gland swelling in a paediatric patient of Rosai-Dorfman disease: A case report
title_short Non surgical management of unilateral lacrimal gland swelling in a paediatric patient of Rosai-Dorfman disease: A case report
title_sort non surgical management of unilateral lacrimal gland swelling in a paediatric patient of rosai dorfman disease a case report
topic Lacrimal gland swelling
Rosai-Dorfman disease
sinus histiocytosis
url http://www.ijo.in/article.asp?issn=0301-4738;year=2019;volume=67;issue=7;spage=1236;epage=1238;aulast=
work_keys_str_mv AT sailieshirodkar nonsurgicalmanagementofunilaterallacrimalglandswellinginapaediatricpatientofrosaidorfmandiseaseacasereport
AT prachipatil nonsurgicalmanagementofunilaterallacrimalglandswellinginapaediatricpatientofrosaidorfmandiseaseacasereport
AT nagendrashah nonsurgicalmanagementofunilaterallacrimalglandswellinginapaediatricpatientofrosaidorfmandiseaseacasereport