Intractable constipation in an adult with megarectosigmoid following repair of low-type anorectal malformation

A 55-year-old male patient received an anoplasty at infancy for low-type anorectal malformation, and intractable constipation was observed since. The patient presented with colitis at the emergency department. Computed tomography revealed feces with a megarectosigmoid of diameter 18 cm. Hirschsprung...

Full description

Bibliographic Details
Main Authors: Yao-Jen Hsu, Yu-Wei Fu, Chin-Hung Wei, Min-Jen Chen
Format: Article
Language:English
Published: Wolters Kluwer Health/LWW 2017-01-01
Series:Formosan Journal of Surgery
Subjects:
Online Access:http://www.e-fjs.org/article.asp?issn=1682-606X;year=2017;volume=50;issue=1;spage=40;epage=43;aulast=Hsu
_version_ 1797706122580197376
author Yao-Jen Hsu
Yu-Wei Fu
Chin-Hung Wei
Min-Jen Chen
author_facet Yao-Jen Hsu
Yu-Wei Fu
Chin-Hung Wei
Min-Jen Chen
author_sort Yao-Jen Hsu
collection DOAJ
description A 55-year-old male patient received an anoplasty at infancy for low-type anorectal malformation, and intractable constipation was observed since. The patient presented with colitis at the emergency department. Computed tomography revealed feces with a megarectosigmoid of diameter 18 cm. Hirschsprung disease was suspected on the basis of the imaging findings. Therefore, a rectal biopsy was performed, which indicated the presence of normal ganglion cells. Bowel management was implemented with one large-volume enema to empty the huge rectal pouch daily. The patient was free of constipation and had an improved nutritional status with appropriate weight gain in 3 months. A laparoscopic Swenson pull-through was performed. The hospital course was uneventful. Enemas, loperamide, and water-soluble fibers were required for frequent soiling because of postoperative hypermotile colon. The treatments were weaned off gradually. At the latest follow-up (2 years postoperatively), the patient had regular voluntary bowel movements with complete bowel control.
first_indexed 2024-03-12T05:47:38Z
format Article
id doaj.art-7f4a684a3c3a427bb81c96ee9ef45948
institution Directory Open Access Journal
issn 1682-606X
language English
last_indexed 2024-03-12T05:47:38Z
publishDate 2017-01-01
publisher Wolters Kluwer Health/LWW
record_format Article
series Formosan Journal of Surgery
spelling doaj.art-7f4a684a3c3a427bb81c96ee9ef459482023-09-03T05:32:25ZengWolters Kluwer Health/LWWFormosan Journal of Surgery1682-606X2017-01-01501404310.4103/fjs.fjs_4_17Intractable constipation in an adult with megarectosigmoid following repair of low-type anorectal malformationYao-Jen HsuYu-Wei FuChin-Hung WeiMin-Jen ChenA 55-year-old male patient received an anoplasty at infancy for low-type anorectal malformation, and intractable constipation was observed since. The patient presented with colitis at the emergency department. Computed tomography revealed feces with a megarectosigmoid of diameter 18 cm. Hirschsprung disease was suspected on the basis of the imaging findings. Therefore, a rectal biopsy was performed, which indicated the presence of normal ganglion cells. Bowel management was implemented with one large-volume enema to empty the huge rectal pouch daily. The patient was free of constipation and had an improved nutritional status with appropriate weight gain in 3 months. A laparoscopic Swenson pull-through was performed. The hospital course was uneventful. Enemas, loperamide, and water-soluble fibers were required for frequent soiling because of postoperative hypermotile colon. The treatments were weaned off gradually. At the latest follow-up (2 years postoperatively), the patient had regular voluntary bowel movements with complete bowel control.http://www.e-fjs.org/article.asp?issn=1682-606X;year=2017;volume=50;issue=1;spage=40;epage=43;aulast=HsuAnorectal malformationsbowel managementconstipationmegarectosigmoidlaparoscopySwenson pull-through
spellingShingle Yao-Jen Hsu
Yu-Wei Fu
Chin-Hung Wei
Min-Jen Chen
Intractable constipation in an adult with megarectosigmoid following repair of low-type anorectal malformation
Formosan Journal of Surgery
Anorectal malformations
bowel management
constipation
megarectosigmoid
laparoscopy
Swenson pull-through
title Intractable constipation in an adult with megarectosigmoid following repair of low-type anorectal malformation
title_full Intractable constipation in an adult with megarectosigmoid following repair of low-type anorectal malformation
title_fullStr Intractable constipation in an adult with megarectosigmoid following repair of low-type anorectal malformation
title_full_unstemmed Intractable constipation in an adult with megarectosigmoid following repair of low-type anorectal malformation
title_short Intractable constipation in an adult with megarectosigmoid following repair of low-type anorectal malformation
title_sort intractable constipation in an adult with megarectosigmoid following repair of low type anorectal malformation
topic Anorectal malformations
bowel management
constipation
megarectosigmoid
laparoscopy
Swenson pull-through
url http://www.e-fjs.org/article.asp?issn=1682-606X;year=2017;volume=50;issue=1;spage=40;epage=43;aulast=Hsu
work_keys_str_mv AT yaojenhsu intractableconstipationinanadultwithmegarectosigmoidfollowingrepairoflowtypeanorectalmalformation
AT yuweifu intractableconstipationinanadultwithmegarectosigmoidfollowingrepairoflowtypeanorectalmalformation
AT chinhungwei intractableconstipationinanadultwithmegarectosigmoidfollowingrepairoflowtypeanorectalmalformation
AT minjenchen intractableconstipationinanadultwithmegarectosigmoidfollowingrepairoflowtypeanorectalmalformation