Acquired smooth muscle hamartoma with sebaceous component
Background: Acquired smooth muscle hamartoma (ASMH) is a rare benign lesion characterized clinically by hyperpigmented plaques with hypertrichosis and some follicular papules. The main histologic finding is the presence of disorganized smooth muscle bundles in the dermis. Only 25 cases of ASMH have...
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| Format: | Article |
| Language: | English |
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Permanyer
2022-01-01
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| Series: | Boletín Médico del Hospital Infantil de México |
| Subjects: | |
| Online Access: | https://www.bmhim.com/frame_esp.php?id=330 |
| _version_ | 1798029317221908480 |
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| author | Eduardo Marín-Hernández Adriana Ramírez-Rico |
| author_facet | Eduardo Marín-Hernández Adriana Ramírez-Rico |
| author_sort | Eduardo Marín-Hernández |
| collection | DOAJ |
| description | Background: Acquired smooth muscle hamartoma (ASMH) is a rare benign lesion characterized clinically by hyperpigmented plaques with hypertrichosis and some follicular papules. The main histologic finding is the presence of disorganized smooth muscle bundles in the dermis. Only 25 cases of ASMH have been reported in the literature. Clinical case: We present the case of an 18-year-old male who reported a pigmented area and increased hair growth on the left hemifacial with one year of evolution. Clinically, a plaque was observed in the preauricular region and on the left cheek with a linear Blaschkoid path, consisting of hyperpigmentation, hypertrichosis, and some papular lesions, with negative pseudo-Darier sign. Histological analysis showed an increase in the number of smooth muscle bundles in the middle and deep dermis surrounding abundant sebaceous glands and numerous hair follicles in different stages of evolution. Conclusions: The sebaceous component in this lesion was prominent. Therefore, we considered this lesion part of a spectrum where the acquired smooth muscle hamartoma and folliculosebaceous cystic hamartoma are found at the extremes. This case would fall in the middle of the range, as it combines both histological features.
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| first_indexed | 2024-04-11T19:23:18Z |
| format | Article |
| id | doaj.art-8971f52b3bc6403c9be53b3e3d299d81 |
| institution | Directory Open Access Journal |
| issn | 0539-6115 |
| language | English |
| last_indexed | 2024-04-11T19:23:18Z |
| publishDate | 2022-01-01 |
| publisher | Permanyer |
| record_format | Article |
| series | Boletín Médico del Hospital Infantil de México |
| spelling | doaj.art-8971f52b3bc6403c9be53b3e3d299d812022-12-22T04:07:15ZengPermanyerBoletín Médico del Hospital Infantil de México0539-61152022-01-0179510.24875/BMHIM.21000177Acquired smooth muscle hamartoma with sebaceous componentEduardo Marín-Hernández0Adriana Ramírez-Rico1Servicio de Dermatología Pediátrica, Unidad Médica de Alta Especialidad, Hospital de Pediatría, Centro Médico Nacional Siglo XXI, Instituto Mexicano del Seguro Social, Mexico City, MexicoServicio de Dermatología, Centro Dermatológico Dr. Ladislao de la Pascua. Mexico City, MexicoBackground: Acquired smooth muscle hamartoma (ASMH) is a rare benign lesion characterized clinically by hyperpigmented plaques with hypertrichosis and some follicular papules. The main histologic finding is the presence of disorganized smooth muscle bundles in the dermis. Only 25 cases of ASMH have been reported in the literature. Clinical case: We present the case of an 18-year-old male who reported a pigmented area and increased hair growth on the left hemifacial with one year of evolution. Clinically, a plaque was observed in the preauricular region and on the left cheek with a linear Blaschkoid path, consisting of hyperpigmentation, hypertrichosis, and some papular lesions, with negative pseudo-Darier sign. Histological analysis showed an increase in the number of smooth muscle bundles in the middle and deep dermis surrounding abundant sebaceous glands and numerous hair follicles in different stages of evolution. Conclusions: The sebaceous component in this lesion was prominent. Therefore, we considered this lesion part of a spectrum where the acquired smooth muscle hamartoma and folliculosebaceous cystic hamartoma are found at the extremes. This case would fall in the middle of the range, as it combines both histological features. https://www.bmhim.com/frame_esp.php?id=330Acquired smooth muscle hamartoma. Sebaceous. Folliculo-sebaceous. |
| spellingShingle | Eduardo Marín-Hernández Adriana Ramírez-Rico Acquired smooth muscle hamartoma with sebaceous component Boletín Médico del Hospital Infantil de México Acquired smooth muscle hamartoma. Sebaceous. Folliculo-sebaceous. |
| title | Acquired smooth muscle hamartoma with sebaceous component |
| title_full | Acquired smooth muscle hamartoma with sebaceous component |
| title_fullStr | Acquired smooth muscle hamartoma with sebaceous component |
| title_full_unstemmed | Acquired smooth muscle hamartoma with sebaceous component |
| title_short | Acquired smooth muscle hamartoma with sebaceous component |
| title_sort | acquired smooth muscle hamartoma with sebaceous component |
| topic | Acquired smooth muscle hamartoma. Sebaceous. Folliculo-sebaceous. |
| url | https://www.bmhim.com/frame_esp.php?id=330 |
| work_keys_str_mv | AT eduardomarinhernandez acquiredsmoothmusclehamartomawithsebaceouscomponent AT adrianaramirezrico acquiredsmoothmusclehamartomawithsebaceouscomponent |