Temporomandibular Joint Prosthesis in a Patient with Congenital Infiltrating Lipomatosis of the Face with Bony Ankylosis of the Temporomandibular Joint: A Case Report
Hemifacial hyperplasia (HFH) is a rare congenital disorder characterized by marked unilateral overgrowth of the facial tissues. A subtype of HFH is congenital infiltrating lipomatosis of the face (CIL-F). This disease is characterized by unilateral diffuse infiltration of mature adipose cells in the...
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MDPI AG
2023-12-01
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| Series: | Journal of Clinical Medicine |
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| author | Lauren C. M. Bulthuis Jean Pierre T. F. Ho Petra C. M. Zuurbier Michail Koutris Jitske W. Nolte Jan de Lange |
| author_facet | Lauren C. M. Bulthuis Jean Pierre T. F. Ho Petra C. M. Zuurbier Michail Koutris Jitske W. Nolte Jan de Lange |
| author_sort | Lauren C. M. Bulthuis |
| collection | DOAJ |
| description | Hemifacial hyperplasia (HFH) is a rare congenital disorder characterized by marked unilateral overgrowth of the facial tissues. A subtype of HFH is congenital infiltrating lipomatosis of the face (CIL-F). This disease is characterized by unilateral diffuse infiltration of mature adipose cells in the facial soft tissue and is associated with skeletal hypertrophy. This work aims to report a case of a CIL-F patient with right facial asymmetry and progressive growth at adolescent age, causing mandibular asymmetry due to signs of concomitant unilateral condylar hyperplasia. At the age of seventeen, a condylectomy was performed to stop the progression of asymmetric mandibular growth. Five years later, the patient developed CIL-F-associated temporomandibular joint ankylosis, manifesting as progressive restricted mouth opening along with temporal facial pain. In this CIL-F patient, a TMJ reconstruction with an alloplastic total joint prosthesis was successfully performed with optimal maximal mouth opening, complete alleviation of temporal facial pain, and stable dental occlusion one year postoperatively. A TMJ reconstruction with a complete alloplastic total joint prosthesis proved to be a predictable, stable, and safe treatment option in a patient with CIL-F-associated TMJ ankylosis who was previously treated with condylectomy due to progressive mandibular asymmetry. |
| first_indexed | 2024-03-08T20:39:10Z |
| format | Article |
| id | doaj.art-b9f6a9f688a34aa586c230bb343adf59 |
| institution | Directory Open Access Journal |
| issn | 2077-0383 |
| language | English |
| last_indexed | 2024-03-08T20:39:10Z |
| publishDate | 2023-12-01 |
| publisher | MDPI AG |
| record_format | Article |
| series | Journal of Clinical Medicine |
| spelling | doaj.art-b9f6a9f688a34aa586c230bb343adf592023-12-22T14:17:33ZengMDPI AGJournal of Clinical Medicine2077-03832023-12-011224772310.3390/jcm12247723Temporomandibular Joint Prosthesis in a Patient with Congenital Infiltrating Lipomatosis of the Face with Bony Ankylosis of the Temporomandibular Joint: A Case ReportLauren C. M. Bulthuis0Jean Pierre T. F. Ho1Petra C. M. Zuurbier2Michail Koutris3Jitske W. Nolte4Jan de Lange5Department of Oral and Maxillofacial Surgery, Amsterdam Universitair Medische Centra, University of Amsterdam, Meibergdreef 9, 1105 AZ Amsterdam, The NetherlandsDepartment of Oral and Maxillofacial Surgery, Amsterdam Universitair Medische Centra, University of Amsterdam, Meibergdreef 9, 1105 AZ Amsterdam, The NetherlandsDepartment of Orthodontics, Academic Centre for Dentistry Amsterdam (ACTA), University of Amsterdam and Vrije Universiteit Amsterdam, 1081 LA Amsterdam, The NetherlandsDepartment of Oral Kinesiology, Academic Centre for Dentistry Amsterdam (ACTA), University of Amsterdam and Vrije Universiteit Amsterdam, 1081 LA Amsterdam, The NetherlandsDepartment of Oral and Maxillofacial Surgery, Amsterdam Universitair Medische Centra, University of Amsterdam, Meibergdreef 9, 1105 AZ Amsterdam, The NetherlandsDepartment of Oral and Maxillofacial Surgery, Amsterdam Universitair Medische Centra, University of Amsterdam, Meibergdreef 9, 1105 AZ Amsterdam, The NetherlandsHemifacial hyperplasia (HFH) is a rare congenital disorder characterized by marked unilateral overgrowth of the facial tissues. A subtype of HFH is congenital infiltrating lipomatosis of the face (CIL-F). This disease is characterized by unilateral diffuse infiltration of mature adipose cells in the facial soft tissue and is associated with skeletal hypertrophy. This work aims to report a case of a CIL-F patient with right facial asymmetry and progressive growth at adolescent age, causing mandibular asymmetry due to signs of concomitant unilateral condylar hyperplasia. At the age of seventeen, a condylectomy was performed to stop the progression of asymmetric mandibular growth. Five years later, the patient developed CIL-F-associated temporomandibular joint ankylosis, manifesting as progressive restricted mouth opening along with temporal facial pain. In this CIL-F patient, a TMJ reconstruction with an alloplastic total joint prosthesis was successfully performed with optimal maximal mouth opening, complete alleviation of temporal facial pain, and stable dental occlusion one year postoperatively. A TMJ reconstruction with a complete alloplastic total joint prosthesis proved to be a predictable, stable, and safe treatment option in a patient with CIL-F-associated TMJ ankylosis who was previously treated with condylectomy due to progressive mandibular asymmetry.https://www.mdpi.com/2077-0383/12/24/7723case reporthemifacial hyperplasiamandibular asymmetryhemimandibular elongationmaxillofacial surgery |
| spellingShingle | Lauren C. M. Bulthuis Jean Pierre T. F. Ho Petra C. M. Zuurbier Michail Koutris Jitske W. Nolte Jan de Lange Temporomandibular Joint Prosthesis in a Patient with Congenital Infiltrating Lipomatosis of the Face with Bony Ankylosis of the Temporomandibular Joint: A Case Report Journal of Clinical Medicine case report hemifacial hyperplasia mandibular asymmetry hemimandibular elongation maxillofacial surgery |
| title | Temporomandibular Joint Prosthesis in a Patient with Congenital Infiltrating Lipomatosis of the Face with Bony Ankylosis of the Temporomandibular Joint: A Case Report |
| title_full | Temporomandibular Joint Prosthesis in a Patient with Congenital Infiltrating Lipomatosis of the Face with Bony Ankylosis of the Temporomandibular Joint: A Case Report |
| title_fullStr | Temporomandibular Joint Prosthesis in a Patient with Congenital Infiltrating Lipomatosis of the Face with Bony Ankylosis of the Temporomandibular Joint: A Case Report |
| title_full_unstemmed | Temporomandibular Joint Prosthesis in a Patient with Congenital Infiltrating Lipomatosis of the Face with Bony Ankylosis of the Temporomandibular Joint: A Case Report |
| title_short | Temporomandibular Joint Prosthesis in a Patient with Congenital Infiltrating Lipomatosis of the Face with Bony Ankylosis of the Temporomandibular Joint: A Case Report |
| title_sort | temporomandibular joint prosthesis in a patient with congenital infiltrating lipomatosis of the face with bony ankylosis of the temporomandibular joint a case report |
| topic | case report hemifacial hyperplasia mandibular asymmetry hemimandibular elongation maxillofacial surgery |
| url | https://www.mdpi.com/2077-0383/12/24/7723 |
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