Chronic pelvic pain due to pelvic lymphangioleiomyomatosis: A case report

Lymphangioleiomyomatosis (LAM), a rare multisystem disease affecting mainly young women, is characterized by an abnormal proliferation of smooth muscle-like cells in the lungs. We report a case of endometriosis with chronic pelvic pain due to pelvic LAM. A 41-year-old gravida 1, para 1 woman had bee...

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Main Authors: Tetsu Wakimoto, Tateki Tsutsui, Mahiru Kawano, Namhyo Kim, Akihiro Moriyama, Tadashi Kimura
Format: Article
Language:English
Published: Wolters Kluwer Medknow Publications 2016-05-01
Series:Gynecology and Minimally Invasive Therapy
Subjects:
Online Access:http://www.sciencedirect.com/science/article/pii/S221330701630003X
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author Tetsu Wakimoto
Tateki Tsutsui
Mahiru Kawano
Namhyo Kim
Akihiro Moriyama
Tadashi Kimura
author_facet Tetsu Wakimoto
Tateki Tsutsui
Mahiru Kawano
Namhyo Kim
Akihiro Moriyama
Tadashi Kimura
author_sort Tetsu Wakimoto
collection DOAJ
description Lymphangioleiomyomatosis (LAM), a rare multisystem disease affecting mainly young women, is characterized by an abnormal proliferation of smooth muscle-like cells in the lungs. We report a case of endometriosis with chronic pelvic pain due to pelvic LAM. A 41-year-old gravida 1, para 1 woman had been experiencing intermittent left pelvic pain for several years. She also complained of dyspnea on effort 2 years previously, and was diagnosed with pulmonary LAM. Abdominal magnetic resonance imaging showed a right ovarian endometriotic cyst and a left pelvic mass. She was referred to our hospital for the treatment of pelvic pain; she underwent laparoscopic cystectomy of the right ovarian endometriotic cyst. Her left pelvic cyst was found in the retroperitoneal space, and biopsy confirmed the diagnosis of LAM. Therefore, we suggest that LAM localized in the pelvis should be considered when a patient with pulmonary LAM presents with pelvic pain or abdominal distention.
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spelling doaj.art-e8a6566ecbf64b7bb655c0a421290b5e2022-12-21T17:56:22ZengWolters Kluwer Medknow PublicationsGynecology and Minimally Invasive Therapy2213-30702016-05-0152848710.1016/j.gmit.2016.02.003Chronic pelvic pain due to pelvic lymphangioleiomyomatosis: A case reportTetsu Wakimoto0Tateki Tsutsui1Mahiru Kawano2Namhyo Kim3Akihiro Moriyama4Tadashi Kimura5Department of Obstetrics and Gynecology, Osaka University Graduate School of Medicine, Osaka, JapanDepartment of Obstetrics and Gynecology, Osaka University Graduate School of Medicine, Osaka, JapanDepartment of Obstetrics and Gynecology, Osaka University Graduate School of Medicine, Osaka, JapanDepartment of Obstetrics and Gynecology, Osaka University Graduate School of Medicine, Osaka, JapanDepartment of Obstetrics and Gynecology, Saiseikai Nakatsu Hospital, Osaka, JapanDepartment of Obstetrics and Gynecology, Osaka University Graduate School of Medicine, Osaka, JapanLymphangioleiomyomatosis (LAM), a rare multisystem disease affecting mainly young women, is characterized by an abnormal proliferation of smooth muscle-like cells in the lungs. We report a case of endometriosis with chronic pelvic pain due to pelvic LAM. A 41-year-old gravida 1, para 1 woman had been experiencing intermittent left pelvic pain for several years. She also complained of dyspnea on effort 2 years previously, and was diagnosed with pulmonary LAM. Abdominal magnetic resonance imaging showed a right ovarian endometriotic cyst and a left pelvic mass. She was referred to our hospital for the treatment of pelvic pain; she underwent laparoscopic cystectomy of the right ovarian endometriotic cyst. Her left pelvic cyst was found in the retroperitoneal space, and biopsy confirmed the diagnosis of LAM. Therefore, we suggest that LAM localized in the pelvis should be considered when a patient with pulmonary LAM presents with pelvic pain or abdominal distention.http://www.sciencedirect.com/science/article/pii/S221330701630003Xlymphangioleiomyomatosispelvic painretroperitoneum
spellingShingle Tetsu Wakimoto
Tateki Tsutsui
Mahiru Kawano
Namhyo Kim
Akihiro Moriyama
Tadashi Kimura
Chronic pelvic pain due to pelvic lymphangioleiomyomatosis: A case report
Gynecology and Minimally Invasive Therapy
lymphangioleiomyomatosis
pelvic pain
retroperitoneum
title Chronic pelvic pain due to pelvic lymphangioleiomyomatosis: A case report
title_full Chronic pelvic pain due to pelvic lymphangioleiomyomatosis: A case report
title_fullStr Chronic pelvic pain due to pelvic lymphangioleiomyomatosis: A case report
title_full_unstemmed Chronic pelvic pain due to pelvic lymphangioleiomyomatosis: A case report
title_short Chronic pelvic pain due to pelvic lymphangioleiomyomatosis: A case report
title_sort chronic pelvic pain due to pelvic lymphangioleiomyomatosis a case report
topic lymphangioleiomyomatosis
pelvic pain
retroperitoneum
url http://www.sciencedirect.com/science/article/pii/S221330701630003X
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