Recurrent idiopathic pulmonary hemosiderosis after long-term remission presented with Sjogren's syndrome: Idiopathic no more?
We report a case of recurrent idiopathic pulmonary hemosiderosis after a long-term remission presented with Sjögren's syndrome. The patient was diagnosed with IPH due to repeated pneumonia and blood sputum in his childhood. He was admitted to our hospital due to exertional dyspnea and dry cough...
| Main Authors: | , , , , , , , , , , |
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| Format: | Article |
| Language: | English |
| Published: |
Elsevier
2018-01-01
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| Series: | Respiratory Medicine Case Reports |
| Online Access: | http://www.sciencedirect.com/science/article/pii/S2213007118301643 |
| _version_ | 1828768677655216128 |
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| author | Toyoshi Yanagihara Yuzo Yamamoto Naoki Hamada Kunihiro Suzuki Saiko Ogata-Suetsugu Eiji Harada Tetsuzo Tagawa Minako Fujiwara Mikiko Hashisako Junya Fukuoka Yoichi Nakanishi |
| author_facet | Toyoshi Yanagihara Yuzo Yamamoto Naoki Hamada Kunihiro Suzuki Saiko Ogata-Suetsugu Eiji Harada Tetsuzo Tagawa Minako Fujiwara Mikiko Hashisako Junya Fukuoka Yoichi Nakanishi |
| author_sort | Toyoshi Yanagihara |
| collection | DOAJ |
| description | We report a case of recurrent idiopathic pulmonary hemosiderosis after a long-term remission presented with Sjögren's syndrome. The patient was diagnosed with IPH due to repeated pneumonia and blood sputum in his childhood. He was admitted to our hospital due to exertional dyspnea and dry cough with bilateral ground-glass opacity in chest computed tomography at the age of 32. Video-assisted thoracoscopic surgery was performed and the specimens showed nonspecific interstitial pneumonia pattern with diffuse, chronic alveolar hemorrhage, suggesting recurrence of IPH. He was also diagnosed with Sjögren's syndrome. Further immunological studies will reveal the pathogenesis of IPH. Keywords: Idiopathic pulmonary hemosiderosis, Sjögren's syndrome |
| first_indexed | 2024-12-11T13:34:49Z |
| format | Article |
| id | doaj.art-f9ca1d6828df43f49e0a187c7e41b1be |
| institution | Directory Open Access Journal |
| issn | 2213-0071 |
| language | English |
| last_indexed | 2024-12-11T13:34:49Z |
| publishDate | 2018-01-01 |
| publisher | Elsevier |
| record_format | Article |
| series | Respiratory Medicine Case Reports |
| spelling | doaj.art-f9ca1d6828df43f49e0a187c7e41b1be2022-12-22T01:05:07ZengElsevierRespiratory Medicine Case Reports2213-00712018-01-01256872Recurrent idiopathic pulmonary hemosiderosis after long-term remission presented with Sjogren's syndrome: Idiopathic no more?Toyoshi Yanagihara0Yuzo Yamamoto1Naoki Hamada2Kunihiro Suzuki3Saiko Ogata-Suetsugu4Eiji Harada5Tetsuzo Tagawa6Minako Fujiwara7Mikiko Hashisako8Junya Fukuoka9Yoichi Nakanishi10Research Institute for Diseases of the Chest, Graduate School of Medical Sciences, Kyushu University, Japan; Corresponding author. Research Institute for Diseases of the Chest, Graduate School of Medical Sciences, Kyushu University, 3-1-1 Maidashi, Higashi-ku, Fukuoka 812-8582, Japan.Research Institute for Diseases of the Chest, Graduate School of Medical Sciences, Kyushu University, JapanResearch Institute for Diseases of the Chest, Graduate School of Medical Sciences, Kyushu University, JapanResearch Institute for Diseases of the Chest, Graduate School of Medical Sciences, Kyushu University, JapanResearch Institute for Diseases of the Chest, Graduate School of Medical Sciences, Kyushu University, JapanResearch Institute for Diseases of the Chest, Graduate School of Medical Sciences, Kyushu University, JapanDepartment of Surgery and Science, Graduate School of Medical Sciences, Kyushu University, JapanDivision of Pathophysiological and Experimental Pathology, Department of Pathology, Graduate School of Medical Sciences, Kyushu University, JapanDepartment of Pathology, Nagasaki University Hospital, Nagasaki University, JapanDepartment of Pathology, Nagasaki University Hospital, Nagasaki University, JapanResearch Institute for Diseases of the Chest, Graduate School of Medical Sciences, Kyushu University, JapanWe report a case of recurrent idiopathic pulmonary hemosiderosis after a long-term remission presented with Sjögren's syndrome. The patient was diagnosed with IPH due to repeated pneumonia and blood sputum in his childhood. He was admitted to our hospital due to exertional dyspnea and dry cough with bilateral ground-glass opacity in chest computed tomography at the age of 32. Video-assisted thoracoscopic surgery was performed and the specimens showed nonspecific interstitial pneumonia pattern with diffuse, chronic alveolar hemorrhage, suggesting recurrence of IPH. He was also diagnosed with Sjögren's syndrome. Further immunological studies will reveal the pathogenesis of IPH. Keywords: Idiopathic pulmonary hemosiderosis, Sjögren's syndromehttp://www.sciencedirect.com/science/article/pii/S2213007118301643 |
| spellingShingle | Toyoshi Yanagihara Yuzo Yamamoto Naoki Hamada Kunihiro Suzuki Saiko Ogata-Suetsugu Eiji Harada Tetsuzo Tagawa Minako Fujiwara Mikiko Hashisako Junya Fukuoka Yoichi Nakanishi Recurrent idiopathic pulmonary hemosiderosis after long-term remission presented with Sjogren's syndrome: Idiopathic no more? Respiratory Medicine Case Reports |
| title | Recurrent idiopathic pulmonary hemosiderosis after long-term remission presented with Sjogren's syndrome: Idiopathic no more? |
| title_full | Recurrent idiopathic pulmonary hemosiderosis after long-term remission presented with Sjogren's syndrome: Idiopathic no more? |
| title_fullStr | Recurrent idiopathic pulmonary hemosiderosis after long-term remission presented with Sjogren's syndrome: Idiopathic no more? |
| title_full_unstemmed | Recurrent idiopathic pulmonary hemosiderosis after long-term remission presented with Sjogren's syndrome: Idiopathic no more? |
| title_short | Recurrent idiopathic pulmonary hemosiderosis after long-term remission presented with Sjogren's syndrome: Idiopathic no more? |
| title_sort | recurrent idiopathic pulmonary hemosiderosis after long term remission presented with sjogren s syndrome idiopathic no more |
| url | http://www.sciencedirect.com/science/article/pii/S2213007118301643 |
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